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Intramedullary Capillary Hemangioma Presenting with Hydrocephalus and Spastic Paraparesis in 2-Month-Old Infant.
World Neurosurg. 2019 05; 125:451-455.WN

Abstract

BACKGROUND

Intramedullary capillary hemangiomas are rare lesions with only 14 cases reported so far and are found in middle-aged persons. Until now only a single case has been reported in the pediatric population. Ours was the second pediatric case and the youngest of all to be diagnosed with an intramedullary capillary hemangioma.

CASE DESCRIPTION

We are reporting the case of a 2-month male child who presented with features of hydrocephalus and spastic paraparesis. On magnetic resonance imaging he had features suggestive of a D10-11 intradural extramedullary lesion and hydrocephalus. We did a ventriculoperitoneal shunt followed by excision of the lesion in the same sitting. Intraoperatively it was found to be an intramedullary lesion, and histopathologic examination showed features suggestive of capillary hemangioma. Postoperatively he recovered well and there is no recurrence 18 months after surgery.

CONCLUSIONS

Intramedullary capillary hemangiomas are extremely rare lesions in infants but should be kept in mind while treating any patient with the spinal lesion. Further reporting of similar cases will help in understanding the natural history, pathogenesis, and management.

Authors+Show Affiliations

Department of Neurosurgery, Fortis Memorial Research Institute Gurugram, Haryana, India. Electronic address: svaishya@hotmail.com.Department of Neurosurgery, Fortis Memorial Research Institute Gurugram, Haryana, India.Department of Neurosurgery, Fortis Memorial Research Institute Gurugram, Haryana, India.Department of Radiology, Fortis Memorial Research Institute Gurugram, Haryana, India.

Pub Type(s)

Case Reports
Journal Article
Review

Language

eng

PubMed ID

30685376

Citation

Vaishya, Sandeep, et al. "Intramedullary Capillary Hemangioma Presenting With Hydrocephalus and Spastic Paraparesis in 2-Month-Old Infant." World Neurosurgery, vol. 125, 2019, pp. 451-455.
Vaishya S, Chauhan A, Patir R, et al. Intramedullary Capillary Hemangioma Presenting with Hydrocephalus and Spastic Paraparesis in 2-Month-Old Infant. World Neurosurg. 2019;125:451-455.
Vaishya, S., Chauhan, A., Patir, R., & Gupta, R. K. (2019). Intramedullary Capillary Hemangioma Presenting with Hydrocephalus and Spastic Paraparesis in 2-Month-Old Infant. World Neurosurgery, 125, 451-455. https://doi.org/10.1016/j.wneu.2019.01.067
Vaishya S, et al. Intramedullary Capillary Hemangioma Presenting With Hydrocephalus and Spastic Paraparesis in 2-Month-Old Infant. World Neurosurg. 2019;125:451-455. PubMed PMID: 30685376.
* Article titles in AMA citation format should be in sentence-case
TY - JOUR T1 - Intramedullary Capillary Hemangioma Presenting with Hydrocephalus and Spastic Paraparesis in 2-Month-Old Infant. AU - Vaishya,Sandeep, AU - Chauhan,Abhishek, AU - Patir,Rana, AU - Gupta,Rakesh K, Y1 - 2019/01/24/ PY - 2018/12/01/received PY - 2019/01/05/revised PY - 2019/01/08/accepted PY - 2019/1/28/pubmed PY - 2019/11/19/medline PY - 2019/1/28/entrez KW - Capillary KW - Hemangiomas KW - Intramedullary KW - Spinal KW - Tumor KW - Vascular SP - 451 EP - 455 JF - World neurosurgery JO - World Neurosurg VL - 125 N2 - BACKGROUND: Intramedullary capillary hemangiomas are rare lesions with only 14 cases reported so far and are found in middle-aged persons. Until now only a single case has been reported in the pediatric population. Ours was the second pediatric case and the youngest of all to be diagnosed with an intramedullary capillary hemangioma. CASE DESCRIPTION: We are reporting the case of a 2-month male child who presented with features of hydrocephalus and spastic paraparesis. On magnetic resonance imaging he had features suggestive of a D10-11 intradural extramedullary lesion and hydrocephalus. We did a ventriculoperitoneal shunt followed by excision of the lesion in the same sitting. Intraoperatively it was found to be an intramedullary lesion, and histopathologic examination showed features suggestive of capillary hemangioma. Postoperatively he recovered well and there is no recurrence 18 months after surgery. CONCLUSIONS: Intramedullary capillary hemangiomas are extremely rare lesions in infants but should be kept in mind while treating any patient with the spinal lesion. Further reporting of similar cases will help in understanding the natural history, pathogenesis, and management. SN - 1878-8769 UR - https://www.unboundmedicine.com/medline/citation/30685376/Intramedullary_Capillary_Hemangioma_Presenting_with_Hydrocephalus_and_Spastic_Paraparesis_in_2_Month_Old_Infant_ L2 - https://linkinghub.elsevier.com/retrieve/pii/S1878-8750(19)30164-0 DB - PRIME DP - Unbound Medicine ER -