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A rare case of autoimmune polyglandular syndrome with Sjögren's syndrome and primary hypoparathyroidism.
BMJ Case Rep 2019; 12(5)BC

Abstract

A 31-year-old woman experienced tetany and was diagnosed with Hashimoto thyroiditis and hypoparathyroidism. At 33 years of age, her renal function gradually decreased. At 39 years of age, she moved to our hospital and was diagnosed with tubulointerstitial nephritis by renal biopsy. Simultaneously, she was diagnosed with Sjögren's syndrome by autoantibodies and salivary gland biopsy. At 40 years of age, based on hypoglycaemia and eosinophilia, she was suspected of adrenal insufficiency, and was diagnosed with primary adrenal insufficiency by both corticotropin stimulation and corticotropin-releasing hormone stimulation test. She was diagnosed as autoimmune polyglandular syndrome (APS) (Hashimoto thyroiditis and possible primary adrenal insufficiency) as well as primary hypoparathyroidism and Sjögren's syndrome, which are very rarely complicated in APS-2. Therefore, in this patient, it was helpful to pay attention for new onset of other autoimmune diseases.

Authors+Show Affiliations

Department of Diabetes and Endocrinology, Graduate School of Medicine, Gifu University, Gifu, Japan.Department of Diabetes and Endocrinology, Graduate School of Medicine, Gifu University, Gifu, Japan.Department of Diabetes and Endocrinology, Graduate School of Medicine, Gifu University, Gifu, Japan.Department of Diabetes and Endocrinology, Graduate School of Medicine, Gifu University, Gifu, Japan.

Pub Type(s)

Journal Article

Language

eng

PubMed ID

31133546

Citation

Iizuka, Katsumi, et al. "A Rare Case of Autoimmune Polyglandular Syndrome With Sjögren's Syndrome and Primary Hypoparathyroidism." BMJ Case Reports, vol. 12, no. 5, 2019.
Iizuka K, Mizuno M, Nonomura K, et al. A rare case of autoimmune polyglandular syndrome with Sjögren's syndrome and primary hypoparathyroidism. BMJ Case Rep. 2019;12(5).
Iizuka, K., Mizuno, M., Nonomura, K., & Yabe, D. (2019). A rare case of autoimmune polyglandular syndrome with Sjögren's syndrome and primary hypoparathyroidism. BMJ Case Reports, 12(5), doi:10.1136/bcr-2018-228634.
Iizuka K, et al. A Rare Case of Autoimmune Polyglandular Syndrome With Sjögren's Syndrome and Primary Hypoparathyroidism. BMJ Case Rep. 2019 May 27;12(5) PubMed PMID: 31133546.
* Article titles in AMA citation format should be in sentence-case
TY - JOUR T1 - A rare case of autoimmune polyglandular syndrome with Sjögren's syndrome and primary hypoparathyroidism. AU - Iizuka,Katsumi, AU - Mizuno,Masami, AU - Nonomura,Kenta, AU - Yabe,Daisuke, Y1 - 2019/05/27/ PY - 2019/5/29/entrez PY - 2019/5/28/pubmed PY - 2019/5/28/medline KW - Sjogren’s syndrome KW - adrenal disorders KW - calcium and bone KW - thyroid disease JF - BMJ case reports JO - BMJ Case Rep VL - 12 IS - 5 N2 - A 31-year-old woman experienced tetany and was diagnosed with Hashimoto thyroiditis and hypoparathyroidism. At 33 years of age, her renal function gradually decreased. At 39 years of age, she moved to our hospital and was diagnosed with tubulointerstitial nephritis by renal biopsy. Simultaneously, she was diagnosed with Sjögren's syndrome by autoantibodies and salivary gland biopsy. At 40 years of age, based on hypoglycaemia and eosinophilia, she was suspected of adrenal insufficiency, and was diagnosed with primary adrenal insufficiency by both corticotropin stimulation and corticotropin-releasing hormone stimulation test. She was diagnosed as autoimmune polyglandular syndrome (APS) (Hashimoto thyroiditis and possible primary adrenal insufficiency) as well as primary hypoparathyroidism and Sjögren's syndrome, which are very rarely complicated in APS-2. Therefore, in this patient, it was helpful to pay attention for new onset of other autoimmune diseases. SN - 1757-790X UR - https://www.unboundmedicine.com/medline/citation/31133546/A_rare_case_of_autoimmune_polyglandular_syndrome_with_Sjögren's_syndrome_and_primary_hypoparathyroidism L2 - https://casereports.bmj.com/cgi/pmidlookup?view=long&pmid=31133546 DB - PRIME DP - Unbound Medicine ER -